Dystonia

INDEX


DYT-ANO3 is a cervical isolated dystonia syndrome1.

Genetics

The majority of ANO3 variants were missense mutations2.

Mode of Inheritance

The condition is autosomal dominant; only heterozygous mutations have been described.

Clinical Presentation2

Median age at onset is 23 years, although there is also a peak in presentation in infancy.
Most patients have multifocal/segmental dystonia, focal or generalized distribution was less common. Cervical dystonia is the most common onset, followed by upper limb.
Axial dystonia is rare.
Dystonic tremor has been described as a key feature of this dystonia, appearing most commonly as head or arm tremor, and may precede the appearance of dystonic postures. Myoclonus is also found commonly.
Generalization has been described in approximately 10% of cases.

Treatment

Standard medical therapies for dystonia; deep brain stimulation is a treatment option.

 

References

  1. Albanese A, Di Giovanni M, Lalli S. Dystonia: diagnosis and management. Eur J Neurol 2019; 26: 5–17.
  2. Lange LM, Junker J, Loens S, Baumann H, Olschewski L, Schaake S, Madoev H, Petkovic S, Kuhnke N, Kasten M, Westenberger A, Domingo A, Marras C, König IR, Camargos S, Ozelius LJ, Klein C, Lohmann K. Genotype-Phenotype Relations for Isolated Dystonia Genes: MDSGene Systematic Review. Mov Disord. 2021 May;36(5):1086-1103.